Poster Presentation Advances in Neuroblastoma Research Congress 2016

Bromodomain-inhibition as therapeutic option for MYCN-amplified neuroblastoma (#179)

Maike Nortmeyer 1 , Emma Bell 1 2 , Chunxuan Shao 3 , Xiaoqi Jiang 4 , Eileen Reinz 5 , Moritz Gartlgruber 1 , Jochen Kreth 1 , Elisa Hess 1 , Volker Ehemann 6 , Johannes Schulte 7 , Frank Westermann 1
  1. Neuroblastoma Genomics, German Cancer Research Center, Heidelberg, Germany
  2. Department of Pathology, University of Cambridge, Cambridge, United Kingdom
  3. Theoretical Systems Biology, German Cancer Research Center, Heidelberg, Germany
  4. Biostatistics, German Cancer Research Center, Heidelberg, Germany
  5. Molecular Genome Analysis, German Cancer Research Center, Heidelberg, Germany
  6. Department of Pathology, University of Heidelberg, Heidelberg, Germany
  7. Department of Paediatric Oncology and Haematology, Charité University Medicine, Berlin, Germany

Background: The BRD4 inhibitor JQ1 inhibits growth and induces apoptosis in a number of MYC-overexpressing cancer types. This study aims to assess the efficacy of JQ1 in neuroblastoma cell lines and to identify the genetic background making neuroblastoma tumors sensitive to JQ1-treatment.

Methods: A panel of 24 neuroblastoma cell lines was screened for JQ1 sensitivity by using Alamar blue viability assays, soft agar assays and FACS live/dead and cell cycle staining. MYCN mRNA and protein levels were determined by quantitative PCR and western blotting.  Reverse Phase Protein Analysis (RPPA) was performed with 15 cell lines. sh/siRNA-mediated knock down of MYCN or BRD4 was used to investigate the relationship between MYCN and BRD4. Global transcript expression was profiled by RNA-seq. ChIP-seq for 6 histone modifications was used to define epigenetic changes upon JQ1 treatment.

Results: Viability screens showed that MYCN-amplified neuroblastoma cell lines are either JQ1 sensitive or resistant, whereas most non-amplified cells show intermediate response to JQ1. Reduced viability was mirrored by the absence of anchorage-independent growth and an increase of G1 and sub G1 fraction after JQ1 treatment. MYCN protein levels were reduced in 6/10 MYCN-amplified cell lines, however, this did not correlate with sensitivity. BRD4 knockdown in IMR5/75 cells did not affect MYCN levels but reduced Cyclin D1 expression. Global expression analysis of IMR5/75 cells emphasizes the importance of TP53-related signaling pathways and cell cycle-regulating genes in the response to JQ1 treatment. This was confirmed by RPPA analysis. Additionally, DNA damage repair genes were up-regulated after 6 and 12 hours JQ1 treatment. RNA expression profiles of JQ1-treated cells and xenograft tumors showed a high correlation. 

Conclusions: JQ1 treatment promotes a G1 arrest and cell death in neuroblastoma cell lines. MYCN-downregulation is not the central mechanism of action. Cell cycle-related genes are affected by JQ1 treatment.